Oral Symptoms of Intractable Ulcerating Enterocolitis of Infancy and Differential Diagnosis: A Case Report

민효선; HYUNG JUN CHOI; JAE HO LEE; Byungjai Choi; Lee Hyo-Seol

doi:10.5933/JKAPD.2014.41.1.80

Intractable ulcerating enterocolitis is an uncommon inflammatory bowel disease syndrome of neonatal onsetfirst described in 1991. Intractable ulcerating enterocolitis usually presents in the neonate with a mouth ulcerationand the subsequent development of perianal disease and colitis. In this case report, an infant, 18 days from birth, with ulcerative lesion on hard palate for systemic differentialdiagnosis about oral lesion is referred from the department depiatrics. At that time, there is no abnormality,except oral lesion-like Aphthous ulcer. The patient was discharged from pediatrics, but returned to the hospital3weeks later with blood diarrhea. As a result of endoscopy, there were large ulcerating lesions and the patientwas diagnosed intractable ulcerating enterocolitis. Early recognition of Intractable ulcerating enterocolitis appears to be beneficial because colectomy, as opposedto immunosuppression, appears to be effective in controlling disease symptoms and progression. Most of theinfants who were affected intractable ulcerating enterocolitis were normal at birth and oral manifestationappeared earlier than others. So, it is very meaningful for dentists to know about Intractable ulcerating enterocolitis.

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* 2022년 이후 발행 논문의 참고문헌은 현재 구축 중입니다.

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